腹部小鼠:腹腔内漂浮囊性淋巴畸形--极为罕见的病例报告。

IF 0.6 Q4 SURGERY
Hamza A Abdul-Hafez, Fathi Milhem, Mohammed Hajhamad
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引用次数: 0

摘要

导言和重要性:淋巴管瘤是一种罕见的良性淋巴畸形,通常发生在头部、颈部或腋窝部位,腹部囊性淋巴畸形(CLM)在成人中尤为罕见。腹部囊性淋巴管畸形占成人所有淋巴管瘤的不到 5%,占所有腹部囊性病变的 7%,发病率约为 25 万分之一。这些病变通常是在影像学检查中意外发现的,没有任何症状。由于没有任何附着物,漂浮在腹腔内,因此其表现形式非常独特:我们报告了一例主诉右上腹痛的 25 岁女性病例。腹部计算机断层扫描(CT)的初步实验室和影像学检查显示有多个来源不明的复杂囊肿。腹腔镜探查术发现了 50 多个大小不一的囊肿,其中一些在腹腔内自由漂浮。医生对所有囊肿进行了完全切除。术后恢复顺利,组织病理学检查确诊为囊性淋巴管瘤:本病例显示了腹腔内多发性、漂浮性和大小不一的囊性淋巴管瘤的不寻常表现,这种罕见的发现给诊断和治疗带来了巨大挑战。腹腔内囊性淋巴管瘤不附着于常见的腹腔内结构,如肠系膜或网膜,使临床表现更加复杂:结论:腹部CLM必须考虑作为可能的诊断,尤其是当囊肿为多发性和复杂性时。自由漂浮的腹部 CLM 可能会导致患者描述的移动肿块症状,这一点必须予以考虑。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Abdominal mouse: Floating intra-abdominal cystic lymphatic malformation - An exceedingly rare case report.

Introduction and importance: Lymphangiomas are rare benign lymphatic malformations, typically affecting the head, neck, or axillary regions, with abdominal cystic lymphatic malformations (CLM) being particularly uncommon in adults. Abdominal CLM account for less than 5 % of all lymphangiomas and 7 % of all abdominal cystic lesions in adults with a prevalence of approximately 1 in 250,000. These lesions are commonly found by accident during imaging investigations and are asymptomatic. Being free of any attachment, floating in the peritoneal cavity make it unique in its presentation.

Case presentation: We report a case of 25-year-old female who complaining of right upper abdominal pain. Initial laboratory and imaging studies by abdominal computed tomography (CT) scan showed multiple complex cysts with undetermined origin. Exploration laparoscopy was performed, revealing over 50 variable-sized cysts, some of them were floating freely within the abdominal cavity. Complete resection of all cysts was performed. Postoperative recovery was uneventful, and histopathological examination confirmed the diagnosis of cystic lymphangiomas.

Clinical discussion: This case demonstrates the unusual presentation of multiple, floating, and variably sized intra-abdominal cystic lymphangiomas, a rare finding that presents significant diagnostic and management challenges. The absence of attachment to common intra-abdominal structures, such as the mesentery or omentum, further complicates the clinical picture.

Conclusion: Abdominal CLM must be considered as possible diagnosis especially if the cysts are multiple and complex. Freely floating abdominal CLM may cause the symptoms of a moving lump described by the patient, which must be taken in consideration.

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来源期刊
CiteScore
1.10
自引率
0.00%
发文量
1116
审稿时长
46 days
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