妊娠期ALDH18A1突变导致鸟氨酸代谢改变,并被伪装成渐冻人症。

Suzanne Quigley, Brian McNamara, Simon Cronin
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引用次数: 0

摘要

常染色体显性遗传性 SPG9A 遗传性痉挛性截瘫的临床发病和恶化,包括可逆性消瘦,已在妊娠期得到描述。SPG9A 是由于 ALDH18A1 基因突变导致脯氨酸和鸟氨酸缺乏所致。我们介绍了一例 29 岁初产妇的病例,她怀孕 32 周时出现上肢肌萎缩性萎缩 6 个月,其背景是 SPG9A 引起的进行性痉挛,但未被发现。分娩后,肌萎缩明显缓解。我们的报告强调了不寻常的临床特征,包括可能提示 SPG9A 的白内障和关节松弛,呼应了与妊娠有关的诱发肌萎缩的现有描述,并记录了饮食干预后两次妊娠的结果。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Alteration in ornithine metabolism due to mutation in ALDH18A1 masquerading as ALS in pregnancy.

Clinical onset and exacerbation of autosomal dominant SPG9A hereditary spastic paraplegia, including reversible wasting, has been described during pregnancy. SPG9A is due to ALDH18A1 mutations resulting in proline and ornithine deficiency. We present the case of a 29 year old primagravida at 32 weeks who presented with six months of upper limb amyotrophic wasting on a background unrecognized progressive spasticity due to SPG9A. The wasting reversed significantly following delivery. Our report highlights the unusual clinical features including cataract and joint laxity which may suggest SPG9A, echoes the existing descriptions of pregnancy-related provocation of amyotrophy in this condition and documents the outcome of two subsequent pregnancies following dietary intervention.

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