Laurie K. Bale , Sally A. West , Naomi M. Gades , Darren J. Baker , Cheryl A. Conover
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However, direct inhibitors of IGF<img>IR signaling are not a viable treatment option for AD due to the essentiality of the IGF<img>IR in physiological growth and metabolism. We have previously demonstrated a more selective means to reduce local IGF<img>IR signaling through inhibition of PAPP-A, a novel zinc metalloprotease that regulates local IGF-I bioavailability through cleavage of inhibitory IGF binding proteins. Here we tested if deletion of PAPP-A in a mouse model of AD provides protection against pathology and behavioral changes. We show that compared to AD mice, AD/PAPP-A KO mice had significantly less plaque burden, reduced astrocytic activation, decreased IGF-IR activity, and improved cognition. Human senile AD plaques showed specific immunostaining for PAPP-A. Thus, inhibition of PAPP-A expression or activity may represent a novel treatment strategy for AD.</div></div>","PeriodicalId":12246,"journal":{"name":"Experimental Neurology","volume":null,"pages":null},"PeriodicalIF":4.6000,"publicationDate":"2024-09-28","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":"0","resultStr":"{\"title\":\"Gene deletion of Pregnancy-associated Plasma Protein-A (PAPP-A) improves pathology and cognition in an Alzheimer's disease mouse model\",\"authors\":\"Laurie K. Bale , Sally A. West , Naomi M. Gades , Darren J. Baker , Cheryl A. Conover\",\"doi\":\"10.1016/j.expneurol.2024.114976\",\"DOIUrl\":null,\"url\":null,\"abstract\":\"<div><div>Alzheimer's disease (AD) is a progressive neurodegenerative disease of age with no effective preventative or treatment approaches. Deeper understanding of the mechanisms underlying the accumulation of toxic β-amyloid oligopeptides and the formation of amyloid plaque in AD has the potential to identify new therapeutic targets. Prior research links the insulin-like growth factor (IGF) system to pathologic mechanisms underlying AD. Suppression of local IGF-I receptor (IGF<img>IR) signaling in AD mice has been shown to reduce plaque formation in the brain and delay neurodegeneration and behavioral changes. However, direct inhibitors of IGF<img>IR signaling are not a viable treatment option for AD due to the essentiality of the IGF<img>IR in physiological growth and metabolism. We have previously demonstrated a more selective means to reduce local IGF<img>IR signaling through inhibition of PAPP-A, a novel zinc metalloprotease that regulates local IGF-I bioavailability through cleavage of inhibitory IGF binding proteins. Here we tested if deletion of PAPP-A in a mouse model of AD provides protection against pathology and behavioral changes. We show that compared to AD mice, AD/PAPP-A KO mice had significantly less plaque burden, reduced astrocytic activation, decreased IGF-IR activity, and improved cognition. Human senile AD plaques showed specific immunostaining for PAPP-A. 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引用次数: 0
摘要
阿尔茨海默病(AD)是一种渐进性老年神经退行性疾病,目前尚无有效的预防或治疗方法。深入了解 AD 中有毒的 β 淀粉样蛋白寡肽的积累和淀粉样斑块的形成机制,有可能发现新的治疗靶点。先前的研究将胰岛素样生长因子(IGF)系统与AD的病理机制联系起来。研究表明,抑制AD小鼠的局部IGF-I受体(IGFIR)信号传导可减少大脑中斑块的形成,延缓神经变性和行为改变。然而,由于 IGFIR 在生理生长和新陈代谢中的重要作用,IGFIR 信号的直接抑制剂并不是治疗 AD 的可行方案。我们之前通过抑制 PAPP-A(一种新型锌金属蛋白酶,可通过裂解抑制性 IGF 结合蛋白调节局部 IGF-I 的生物利用度)证明了一种更具选择性的减少局部 IGFIR 信号传导的方法。在这里,我们测试了在 AD 小鼠模型中删除 PAPP-A 是否能保护小鼠免受病理和行为变化的影响。我们发现,与注意力缺失症小鼠相比,AD/PAPP-A KO 小鼠的斑块负担明显减轻,星形胶质细胞活化减少,IGF-IR 活性降低,认知能力提高。人类老年 AD 斑块显示出 PAPP-A 的特异性免疫染色。因此,抑制PAPP-A的表达或活性可能是治疗AD的一种新策略。
Gene deletion of Pregnancy-associated Plasma Protein-A (PAPP-A) improves pathology and cognition in an Alzheimer's disease mouse model
Alzheimer's disease (AD) is a progressive neurodegenerative disease of age with no effective preventative or treatment approaches. Deeper understanding of the mechanisms underlying the accumulation of toxic β-amyloid oligopeptides and the formation of amyloid plaque in AD has the potential to identify new therapeutic targets. Prior research links the insulin-like growth factor (IGF) system to pathologic mechanisms underlying AD. Suppression of local IGF-I receptor (IGFIR) signaling in AD mice has been shown to reduce plaque formation in the brain and delay neurodegeneration and behavioral changes. However, direct inhibitors of IGFIR signaling are not a viable treatment option for AD due to the essentiality of the IGFIR in physiological growth and metabolism. We have previously demonstrated a more selective means to reduce local IGFIR signaling through inhibition of PAPP-A, a novel zinc metalloprotease that regulates local IGF-I bioavailability through cleavage of inhibitory IGF binding proteins. Here we tested if deletion of PAPP-A in a mouse model of AD provides protection against pathology and behavioral changes. We show that compared to AD mice, AD/PAPP-A KO mice had significantly less plaque burden, reduced astrocytic activation, decreased IGF-IR activity, and improved cognition. Human senile AD plaques showed specific immunostaining for PAPP-A. Thus, inhibition of PAPP-A expression or activity may represent a novel treatment strategy for AD.
期刊介绍:
Experimental Neurology, a Journal of Neuroscience Research, publishes original research in neuroscience with a particular emphasis on novel findings in neural development, regeneration, plasticity and transplantation. The journal has focused on research concerning basic mechanisms underlying neurological disorders.