遗传性慢性胆汁淤积性肝病:综述。

IF 3.1 3区 医学 Q2 GASTROENTEROLOGY & HEPATOLOGY
Jasmine Tidwell, George Y Wu
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引用次数: 0

摘要

由于遗传原因导致的慢性胆汁淤积症通常在儿童时期就能确诊。不过,许多病例可在成年后发病并存活。病程长短因病因不同而有很大差异。实验室数据通常显示共轭高胆红素血症、碱性磷酸酶和γ-谷氨酰转肽酶升高。患者可能没有症状,但一旦出现,典型的症状是瘙痒、黄疸、乏力和酒样便。诊断方法和所需的治疗取决于潜在的病因。随着全基因组关联研究的发展,人们得以确定与胆汁淤积性肝病病理生理学相关的特定基因突变。本综述旨在强调慢性胆汁淤积性肝病的遗传学、临床病理生理学、表现、诊断和治疗。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Heritable Chronic Cholestatic Liver Diseases: A Review.

Chronic cholestasis due to heritable causes is usually diagnosed in childhood. However, many cases can present and survive into adulthood. The time course varies considerably depending on the underlying etiology. Laboratory data usually reveal elevated conjugated hyperbilirubinemia, alkaline phosphatase, and gamma-glutamyl transpeptidase. Patients may be asymptomatic; however, when present, the typical symptoms are pruritus, jaundice, fatigue, and alcoholic stools. The diagnostic methods and management required depend on the underlying etiology. The development of genome-wide associated studies has allowed the identification of specific genetic mutations related to the pathophysiology of cholestatic liver diseases. The aim of this review was to highlight the genetics, clinical pathophysiology, presentation, diagnosis, and treatment of heritable etiologies of chronic cholestatic liver disease.

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来源期刊
Journal of Clinical and Translational Hepatology
Journal of Clinical and Translational Hepatology GASTROENTEROLOGY & HEPATOLOGY-
CiteScore
6.40
自引率
2.80%
发文量
496
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