一种导致中国人显性β-地中海贫血的新型 HBB 框状位移突变

IF 1.2 4区 医学 Q4 BIOCHEMISTRY & MOLECULAR BIOLOGY
Cuili Yao, Long Chen, Jingting Ma, Na Li, Jiang Lin, Lina Huang, Yani Lin, Jun Xue
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引用次数: 0

摘要

我们报告了一名罕见的β地中海贫血患者,他是一名41岁的中国男性,主要临床症状为小细胞色素减退性贫血、黄疸和脾肿大。通过下一代测序(NGS),我们发现了一个新的HBB基因突变(c.358_365dup, p.Phe123Alafs*39),该突变导致β-球蛋白链异常延长,由159个氨基酸残基组成。β-球蛋白的二级和三维结构预测,新型延长的β-球蛋白链在血红蛋白中具有相当大的不稳定性风险,并导致临床表型。这项研究有助于丰富地中海贫血遗传致病基因突变数据库,并强调了 NGS 在地中海贫血家族基因突变筛查中的重要意义。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
A Novel Frameshift Mutation of HBB Causing Dominant β-Thalassemia in a Chinese Individual.

We reported a rare β-thalassemia patient, a 41-year-old Chinese male with small cell hypopigmentation anemia, jaundice and splenomegaly as the main clinical symptoms. By using Next-Generation Sequencing (NGS), we identified a novel de novo HBB mutation(c.358_365dup, p.Phe123Alafs*39) which resulted in an abnormally prolonged β-globin chain comprising 159 amino acid residues. The secondary and three-dimensional structures of the β-globin predicted that the novel prolonged β-globin chain has a considerable risk of instability in the hemoglobin, and leads to clinical phenotype. This study contributes to the enrichment of the genetic pathogenic mutation database for thalassemia and underscores the significance of NGS in the screening of mutations for thalassemia families.

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来源期刊
Hemoglobin
Hemoglobin 医学-生化与分子生物学
CiteScore
1.70
自引率
10.00%
发文量
59
审稿时长
3 months
期刊介绍: Hemoglobin is a journal in the English language for the communication of research and information concerning hemoglobin in humans and other species. Hemoglobin publishes articles, reviews, points of view The journal covers topics such as: structure, function, genetics and evolution of hemoglobins biochemical and biophysical properties of hemoglobin molecules characterization of hemoglobin disorders (variants and thalassemias), consequences and treatment of hemoglobin disorders epidemiology and prevention of hemoglobin disorders (neo-natal and adult screening) modulating factors methodology used for diagnosis of hemoglobin disorders
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