Eros Qama, Kritika Krishnamurthy, Joseph J Mulvey, Kenneth G Liu, David L Fernandes, Yanan Fang
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引用次数: 0
摘要
先天性因子缺乏症(如血友病 A)也有眼底出血的记录,但凝血酶原缺乏症从未有过眼底出血的记录。这里,我们描述了一例不寻常的病例,一名 67 岁的妇女在咳嗽发作后,因视网膜下出血导致右眼视力突然下降。值得注意的是,该患者 12 年前曾在类似情况下因视网膜下出血接受了左眼去核手术。在问诊过程中,医生发现患者有凝血酶原缺乏症病史,随后通过实验室检测证实了这一点。除了反复眼底出血和一次儿童时期拔牙后出血外,患者没有其他出血史。随后的分子研究发现,该患者的 G1499A(Arg500Gln)处存在同卵错义突变,该变异先前被鉴定为 R457Q。虽然凝血酶原缺乏引发视网膜下出血的可能性很低,但它很可能会加重视网膜出血,导致出血难以控制。对眼底出血患者进行全面的凝血检查至关重要。对于凝血酶原时间和活化部分凝血活酶时间不同程度延长并在混合研究中进行校正的患者,应测定 II 因子活性。对于凝血酶原水平单独偏低的患者,建议进行基因测序和家族研究等其他检查。
Prothrombin deficiency with recurrent subretinal hemorrhage.
Ocular hemorrhage has been recorded in congenital factor deficiencies like hemophilia A, but it has never been documented in prothrombin deficiency. Here, we describe an unusual case of sudden vision loss in the right eye caused by subretinal hemorrhage following a coughing episode in a 67-year-old woman. Notably, the patient underwent left eye enucleation 12 years previously under similar circumstances due to subretinal hemorrhage. During the interview, it was discovered that the patient had a history of prothrombin deficiency, which was subsequently confirmed through laboratory testing. Aside from recurrent ocular bleeding and 1 instance of bleeding following dental extraction in childhood, there is no other history of bleeding. Subsequent molecular studies revealed a homozygous missense mutation at G1499A (Arg500Gln), a variant previously identified as R457Q. Although the likelihood of prothrombin deficiency initiating subretinal hemorrhage is low, it is likely to worsen retinal hemorrhage and contribute to difficulty in controlling bleeding. A comprehensive coagulation workup is essential in patients with ocular hemorrhage. Determining factor II activity should be included in individuals exhibiting variably prolonged prothrombin time and activated partial thromboplastin time with correction in mixing studies. Additional investigations, such as genetic sequencing and family studies, are advised for those with isolated low prothrombin levels.