关于软骨细胞 TRIM37 下调的蛋白质组学研究:对 MULIBREY 综合征的影响。

IF 3.5 2区 医学 Q2 ENDOCRINOLOGY & METABOLISM
Bone Pub Date : 2024-07-15 DOI:10.1016/j.bone.2024.117205
Benjamin Brigant , Valérie Metzinger-Le Meuth , Victor Boyartchuk , Hakim Ouled-Haddou , Ida Chiara Guerrera , Jacques Rochette , Laurent Metzinger
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引用次数: 0

摘要

由TRIM37常染色体隐性突变引起的多发性骨骼发育不良会影响骨骼发育,导致生长发育迟缓,并在多个器官出现并发症。在这项研究中,我们采用蛋白质组学和 qPCR 联合筛选方法,通过比较 CHON-002 野生型(WT)细胞和 CHON-002 TRIM37 基因敲除(KD)细胞,研究了 CHON-002 细胞系的分子变化。我们的蛋白质组学分析表明,TRIM37 缺失主要影响细胞外基质蛋白(ECM)的表达。具体来说,纳米液相色谱-质谱/质谱(nanoLC-MS/MS)实验显示,SPARC和胶原蛋白产物(COL1A1、COL3A1、COL5A1)的上调是对TRIM37 KD的反应。同时,针对成骨相关基因的大规模 qPCR 检测证实了 SPARC 在 mRNA 水平上的失调。基因本体富集分析强调了参与 ECM 组织和 TGF-β 信号通路的失调蛋白,这表明 TRIM37 在维持 ECM 完整性和调节软骨细胞增殖方面发挥作用。这些研究结果表明,软骨细胞中 TRIM37 的缺乏会改变 ECM 蛋白的组成,并可能影响长骨的生长,从而导致 MULIBREY 纳米病的病理生理学。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

A proteomic study of the downregulation of TRIM37 on chondrocytes: Implications for the MULIBREY syndrome

A proteomic study of the downregulation of TRIM37 on chondrocytes: Implications for the MULIBREY syndrome

MULIBREY nanism which results from autosomal recessive mutations in TRIM37 impacts skeletal development, leading to growth delay with complications in multiple organs. In this study, we employed a combined proteomics and qPCR screening approach to investigate the molecular alterations in the CHON-002 cell line by comparing CHON-002 wild-type (WT) cells to CHON-002 TRIM37 knockdown (KD) cells. Our proteomic analysis demonstrated that TRIM37 depletion predominantly affects the expression of extracellular matrix proteins (ECM). Specifically, nanoLC-MS/MS experiments revealed an upregulation of SPARC, and collagen products (COL1A1, COL3A1, COL5A1) in response to TRIM37 KD. Concurrently, large-scale qPCR assays targeting osteogenesis-related genes corroborated these dysregulations of SPARC at the mRNA level. Gene ontology enrichment analysis highlighted the involvement of dysregulated proteins in ECM organization and TGF-β signaling pathways, indicating a role for TRIM37 in maintaining ECM integrity and regulating chondrocyte proliferation. These findings suggest that TRIM37 deficiency in chondrocytes change ECM protein composition and could impairs long bone growth, contributing to the pathophysiology of MULIBREY nanism.

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来源期刊
Bone
Bone 医学-内分泌学与代谢
CiteScore
8.90
自引率
4.90%
发文量
264
审稿时长
30 days
期刊介绍: BONE is an interdisciplinary forum for the rapid publication of original articles and reviews on basic, translational, and clinical aspects of bone and mineral metabolism. The Journal also encourages submissions related to interactions of bone with other organ systems, including cartilage, endocrine, muscle, fat, neural, vascular, gastrointestinal, hematopoietic, and immune systems. Particular attention is placed on the application of experimental studies to clinical practice.
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