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引用次数: 0
摘要
溶酶体贮积症是一组罕见的遗传性代谢疾病。由于溶酶体酶的缺乏,复杂的底物会积聚在不同器官的溶酶体中。根据受影响酶的不同,会导致临床上不同的慢性进行性多器官疾病。诊断往往被延迟。由于临床症状包括肌肉骨骼系统,溶酶体贮积症对(儿科)风湿病学家具有重要意义。本文主要介绍粘多糖病 I-S 型、粘脂病 III 型、戈谢病和法布里病。怀疑溶酶体贮积病时,应测定干血斑或白细胞中的酶活性。对于某些疾病,还可以对特定的生物标志物进行分析。应通过基因检测来确诊。由于上述三种疾病都有相应的治疗方案,因此及时诊断非常重要。
[Importance of lysosomal storage diseases in rheumatology].
Lysosomal storage diseases are a group of rare hereditary metabolic diseases. Due to a deficiency of lysosomal enzymes, complex substrates accumulate in the lysosomes of various organs. Depending on the affected enzyme, this results in clinically variable and chronic progressive multiorgan diseases. Diagnosis is often delayed. As clinical symptoms include the musculoskeletal system, an awareness of lysosomal storage diseases is of relevance to (pediatric) rheumatologists. This article is focused on Mucopolysaccharidosis type I‑S, Mucolipidosis type III, Gaucher disease and Fabry disease. When suspecting a lysosomal storage disease, enzyme activity should be determined in dried blood spots or leukocytes. For some diseases, specific biomarkers can additionally be analyzed. Diagnosis should be confirmed by genetic testing. As causal treatment options are available for three of the presented diseases, a timely diagnosis is very important.
期刊介绍:
Die Zeitschrift für Rheumatologie ist ein international angesehenes Publikationsorgan und dient der Fortbildung von niedergelassenen und in der Klinik tätigen Rheumatologen. Die Zeitschrift widmet sich allen Aspekten der klinischen Rheumatologie, der Therapie rheumatischer Erkrankungen sowie der rheumatologischen Grundlagenforschung.
Umfassende Übersichtsarbeiten zu einem aktuellen Schwerpunktthema sind das Kernstück jeder Ausgabe. Im Mittelpunkt steht dabei gesichertes Wissen zu Diagnostik und Therapie mit hoher Relevanz für die tägliche Arbeit – der Leser erhält konkrete Handlungsempfehlungen.
Frei eingereichte Originalien ermöglichen die Präsentation wichtiger klinischer Studien und dienen dem wissenschaftlichen Austausch.