原发性皮肤 NUT 癌:4 例病例的临床病理学和遗传学研究。

IF 4.5 1区 医学 Q1 PATHOLOGY
American Journal of Surgical Pathology Pub Date : 2024-08-01 Epub Date: 2024-05-06 DOI:10.1097/PAS.0000000000002240
Keisuke Goto, Yoji Kukita, Tsunekazu Hishima, Shigeto Matsushita, Takuji Tsuyuki, Kosuke Makihara, Kaori Koga, Shoko Mukumoto, Keiichiro Honma
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引用次数: 0

摘要

世卫组织皮肤肿瘤分类第五版(2023 年)新近描述了原发性皮肤 NUT 癌,但有关该癌症类型的信息仍然很少。在此,我们对 4 例病例进行了临床病理学和遗传学分析。其中包括四名老年女性(中位年龄 77 岁,年龄范围:68 至 82 岁)。肿瘤大小中位数为 12.5(10 至 40 毫米)。肿瘤位于头皮、太阳穴、大腿和手掌。两名患者(50%)出现区域淋巴结转移。在10.5(3至15)个月的随访期间,未发现远处转移或死亡病例。桑格(Sanger)DNA和全外显子组RNA测序发现了BRD3::NUTM1(2例)和BRD4::NUTM1(2例)融合。BRD3重组肿瘤的组织学显示表皮连接、肿瘤巢相对较小、导管或细胞质内腔形成,而BRD4重组肿瘤的组织学显示由盘状肿瘤细胞组成的大实性巢。在所有(100%)肿瘤中,NUT、细胞角蛋白、p63、EMA、TRPS1、c-MYB、CD56和INSM1均有不同程度的免疫表达。此外,弥漫性 SOX10 表达也很常见(3/4,75%)。对之前描述过的五个病例的文献回顾显示,女性占多数,无复发,BRD3::NUTM1融合频繁,组织学为导管腺结构。我们的研究结果和文献表明,原发性皮肤 NUT 癌以老年女性为主,BRD3::NUTM1 融合相对频繁,组织病理学呈腺管状分化,无突然角化,免疫谱特征与其他器官不同。在有限的随访中,所有病例均未出现远处转移或与疾病相关的死亡。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Primary Cutaneous NUT Carcinoma: Clinicopathologic and Genetic Study of 4 Cases.

WHO Classification of Skin Tumors, fifth edition (2023) has newly described primary cutaneous NUT carcinoma; however, information on this cancer type remains scarce. Herein, we performed clinicopathologic and genetic analyses of 4 cases. Four elderly women (median age 77 y, range: 68 to 82 y) were included. The median tumor size was 12.5 (10 to 40 mm). Tumors were located on the scalp, temple, thigh, and palm. Two (50%) patients presented with regional lymph node metastases. Neither distant metastasis nor mortality was observed during patient follow-up of 10.5 (3 to 15) months. Sanger, panel DNA and whole-exome RNA sequencing revealed BRD3::NUTM1 (n=2) and BRD4::NUTM1 (n=2) fusions. Histology of BRD3 -rearranged tumors revealed an epidermal connection, relatively small tumor nests, and ductal or intracytoplasmic luminal formation, whereas that of BRD4 -rearranged tumors revealed large solid nests comprising discohesive tumor cells. NUT, cytokeratins, p63, EMA, TRPS1, c-MYB, CD56, and INSM1 were immunoexpressed to varying degrees in all (100%) tumors. Furthermore, diffuse SOX10 expression was common (3/4, 75%). The literature review of five previously described cases revealed women predominance, no recurrence, frequent BRD3::NUTM1 fusions, and histology of ductoglandular structures. Our study findings and literature suggest elderly women predominance, relatively frequent BRD3::NUTM1 fusions, histopathologic ductoglandular differentiation, absence of abrupt keratinisation, and a characteristic immunoprofile in primary cutaneous NUT carcinoma, unlike in that of other organ. No distant metastasis or disease-associated mortality was seen in all cases with limited follow-up.

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来源期刊
CiteScore
10.30
自引率
5.40%
发文量
295
审稿时长
1 months
期刊介绍: The American Journal of Surgical Pathology has achieved worldwide recognition for its outstanding coverage of the state of the art in human surgical pathology. In each monthly issue, experts present original articles, review articles, detailed case reports, and special features, enhanced by superb illustrations. Coverage encompasses technical methods, diagnostic aids, and frozen-section diagnosis, in addition to detailed pathologic studies of a wide range of disease entities. Official Journal of The Arthur Purdy Stout Society of Surgical Pathologists and The Gastrointestinal Pathology Society.
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