反义寡核苷酸介导的 IGFBPs 下调可增强 IGF-1 信号传导。

IF 3.2 4区 医学 Q2 CLINICAL NEUROLOGY
Alper Yavas, Maaike van Putten, Annemieke Aartsma-Rus
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引用次数: 0

摘要

胰岛素样生长因子-1(IGF-1)可刺激肌肉再生、生长和功能,因此被认为是包括杜兴氏肌肉萎缩症在内的肌肉萎缩症的治疗药物。目前已进行了多项临床前和临床研究,以显示 IGF-1 的治疗潜力,然而,给药问题、半衰期短和同工酶的复杂性都给研究带来了挑战。反义寡核苷酸(AONs)能够通过干扰靶蛋白的转录本来下调靶蛋白。在这里,我们研究了通过下调 IGF 结合蛋白来增强 IGF-1 信号转导的可行性。我们观察到,Igfbp1 和 Igfbp3 的缺框外显子跳越下调了它们的蛋白表达,从而增加了体外 IGF-1 信号下游的 Akt 磷酸化。3'RNA测序分析揭示了C2C12细胞中相关转录组对IGFBP3下调的反应。然而,经过 6 周的全身治疗后,AONs 并未在 mdx 小鼠体内诱导任何外显子跳转或蛋白敲除。我们得出的结论是,IGFBP 下调可能是增加 IGF-1 信号传导的一个好策略,但要在体内有效传递和敲除 IGFBP,还需要其他工具。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Antisense Oligonucleotide-Mediated Downregulation of IGFBPs Enhances IGF-1 Signaling.

Insulin-like growth factor-1 (IGF-1) has been considered as a therapeutic agent for muscle wasting conditions including Duchenne muscular dystrophy as it stimulates muscle regeneration, growth and function. Several preclinical and clinical studies have been conducted to show the therapeutic potential of IGF-1, however, delivery issues, short half-life and isoform complexity have impose challenges. Antisense oligonucleotides (AONs) are able to downregulate target proteins by interfering with their transcripts. Here, we investigated the feasibility of enhancing IGF-1 signaling by downregulation of IGF-binding proteins. We observed that out of frame exon skipping of Igfbp1 and Igfbp3 downregulated their protein expression, which increased Akt phosphorylation on the downstream IGF-1 signaling in vitro. 3'RNA sequencing analysis revealed the related transcriptome in C2C12 cells in response to IGFBP3 downregulation. The AONs did however not induce any exon skipping or protein knockdown in mdx mice after 6 weeks of systemic treatment. We conclude that IGFBP downregulation could be a good strategy to increase IGF-1 signaling but alternative tools are needed for efficient delivery and knockdown in vivo.

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来源期刊
Journal of neuromuscular diseases
Journal of neuromuscular diseases Medicine-Neurology (clinical)
CiteScore
5.10
自引率
6.10%
发文量
102
期刊介绍: The Journal of Neuromuscular Diseases aims to facilitate progress in understanding the molecular genetics/correlates, pathogenesis, pharmacology, diagnosis and treatment of acquired and genetic neuromuscular diseases (including muscular dystrophy, myasthenia gravis, spinal muscular atrophy, neuropathies, myopathies, myotonias and myositis). The journal publishes research reports, reviews, short communications, letters-to-the-editor, and will consider research that has negative findings. The journal is dedicated to providing an open forum for original research in basic science, translational and clinical research that will improve our fundamental understanding and lead to effective treatments of neuromuscular diseases.
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