男性青春期和成年期鸟氨酸转氨基甲酰基酶缺乏症。

Enzyme Pub Date : 1990-01-01 DOI:10.1159/000468724
M Yoshino, J Nishiyori, F Yamashita, R Kumashiro, H Abe, K Tanikawa, T Ohno, K Nakao, N Kaku, H Fukushima
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引用次数: 33

摘要

在58岁、46岁和17岁的男性患者中发现肝鸟氨酸转氨基甲酰基酶(OTC)的离散缺乏症。两人均出现高氨血症昏迷。17岁患者的母亲和妹妹自发或在蛋白加载后表现出嗜酸性尿,因此显示出杂合性。另一名患者的妹妹和第三名患者的女儿在蛋白质负荷后表现出较小的口腔酸尿。这些观察结果表明,成年男性患者高氨血症状态的鉴别诊断应包括遗传性OTC缺乏。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Ornithine transcarbamylase deficiency in male adolescence and adulthood.

A discrete deficiency of hepatic ornithine transcarbamylase (OTC) was found in male patients who were 58, 46 and 17 years old. Each had developed hyperammonemic coma. The mother and a sister of the 17-year-old patient exhibited orotic aciduria either spontaneously or after protein loading, thus demonstrating heterozygosity. A sister of one other patient and a daughter of the third patient showed a smaller orotic aciduria after protein loading. These observations indicate that inherited deficiency of OTC should be included in the differential diagnosis of hyperammonemic states in adult male patients.

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