局限于面部的木穴线状萎缩皮病:一种极为罕见的疾病

T. Arif
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引用次数: 0

摘要

简介:线性Moulin萎缩皮病(LAM)是一种罕见的皮肤病,其特征是Blaschko线(BL)后色素沉着的萎缩斑块。躯干和四肢是最常见的受累部位。孤立的面部病变是非常罕见的。尽管进行了全面的医学文献检索,但笔者只发现两例LAM的病变完全局限于面部。在这篇文章中,作者提出了第三个仅局限于面部的LAM案例。病例介绍:一名26岁男性,自诉左侧鼻及眉间区多处线性非瘙痒性色素性病变,持续6个月。没有红斑史,皮肤增厚/硬化,或病灶周围的紫色边界。临床检查发现多发色素沉着的褐色病变,多数为凹陷性病变,累及左侧鼻翼、鼻梁及眉间区,呈Blaschkoid型。LAM的诊断基于病史和临床检查。结论:LAM是一种罕见的疾病,面部定位使其极为罕见。当面部出现blasch样样的色素沉着性凹陷病变时,应将其列入鉴别诊断。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Linear Atrophoderma of Moulin Localized to Face: An Exceedingly Rare Entity
Introduction: Linear atrophoderma of Moulin (LAM) is a rare dermatologic disorder characterized by hyperpigmented atrophic plaques following the Blaschko lines (BL). The trunk and limbs are the usual sites affected. Isolated facial involvement is an exceedingly rare entity. Despite a comprehensive medical literature search, the author could find only two cases of LAM where the lesions are exclusively localized to the face. In this article, the author presents the third case of LAM localized to face only. Case Presentation: A 26-year-old male complained of multiple linear non-pruritic pigmented lesions over the left side of the nose and glabellar area of six months’ duration. There was no history of erythema, thickening/hardening of skin, or violaceous border surrounding the lesions. On clinical examination, there were multiple hyperpigmented brownish lesions, the majority of which were depressed, involving the left ala and bridge of nose laterally and glabellar area in a Blaschkoid pattern. Diagnosis of LAM was established based on suggestive history and clinical examination. Conclusions: LAM is a rare disorder, and the facial localization makes it exceedingly rare. It should be kept in the differential diagnosis when hyperpigmented depressed lesions are present in a Blaschkoid pattern on the face.
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