评估基因治疗作为治疗严重血友病的潜在范式转变。

IF 5.4 2区 医学 Q1 IMMUNOLOGY
Courtney D Thornburg, Dana H Simmons, Annette von Drygalski
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引用次数: 1

摘要

血友病的特点是凝血因子VIII或IX缺乏。严重血友病的一般护理标准是经常静脉注射重组或血浆源性因子替代以防止出血。虽然这种治疗在预防出血方面是有效的,但频繁的输液对患者来说是负担。不坚持治疗方案会使血友病患者面临自发性和创伤性关节出血以及危及生命的出血(如颅内出血)的风险。这种疾病的慢性往往导致目标关节的形成,造成长期疼痛和损害活动能力。血友病是一种单基因遗传病,其遗传学已被充分理解,是实施基因治疗创新的理想疾病。事实上,最近批准的两种基因治疗产品有可能改变血友病的治疗模式。valoccogene roxaparvovec和etrancogene dezaparvovec-drlb分别是用于血友病A和B的基因疗法。这些治疗,作为单次静脉输注,可以改善患者的生活质量,减少治疗负担,并导致因子表达,实际上消除了对因子替代的需要。由于这两种治疗都涉及针对肝脏的病毒载体,因此短期和长期的安全性和有效性监测包括监测肝酶以跟踪肝脏健康。目前正在进行疗效、基因表达持久性和安全性的长期监测。基因治疗为血友病患者提供了一种有希望的新治疗选择,值得继续创新和研究。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Evaluating Gene Therapy as a Potential Paradigm Shift in Treating Severe Hemophilia.

Hemophilia is characterized by a deficiency in coagulation factors VIII or IX. The general standard of care for severe hemophilia is frequent intravenous recombinant or plasma-derived factor replacement to prevent bleeding. While this treatment is effective in preventing bleeding, frequent infusions are burdensome for patients. Nonadherence to the therapeutic regimen leaves people with hemophilia at risk for spontaneous and traumatic bleeds into joints as well as life-threatening bleeds such as intracranial hemorrhage. The chronicity of the disorder often leads to the formation of target joints, causing long-term pain and impairing mobility. As a monogenic disorder with well-understood genetics, hemophilia is an ideal disorder for implementing innovations in gene therapies. Indeed, recent approvals of two gene therapy products have the potential to shift the hemophilia treatment paradigm. Valoctocogene roxaparvovec and etranacogene dezaparvovec-drlb are gene therapies for hemophilia A and B, respectively. These therapies, given as a single intravenous infusion, may improve patients' quality of life, decreasing treatment burden and resulting in factor expression that virtually eliminates the need for factor replacement. Since both treatments involve viral vectors targeted to the liver, short- and long-term safety and efficacy monitoring involves monitoring liver enzymes to track liver health. Long-term monitoring of efficacy, durability of gene expression, and safety are ongoing. Gene therapy presents a promising new therapeutic option for patients with hemophilia and warrants continued innovation and investigation.

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来源期刊
BioDrugs
BioDrugs 医学-免疫学
CiteScore
12.60
自引率
2.90%
发文量
50
审稿时长
>12 weeks
期刊介绍: An essential resource for R&D professionals and clinicians with an interest in biologic therapies. BioDrugs covers the development and therapeutic application of biotechnology-based pharmaceuticals and diagnostic products for the treatment of human disease. BioDrugs offers a range of additional enhanced features designed to increase the visibility, readership and educational value of the journal’s content. Each article is accompanied by a Key Points summary, giving a time-efficient overview of the content to a wide readership. Articles may be accompanied by plain language summaries to assist patients, caregivers and others in understanding important medical advances. The journal also provides the option to include various other types of enhanced features including slide sets, videos and animations. All enhanced features are peer reviewed to the same high standard as the article itself. Peer review is conducted using Editorial Manager®, supported by a database of international experts. This database is shared with other Adis journals.
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