CRISPR-Cas9基因组编辑治疗杜氏肌营养不良症的传递挑战。

IF 2.9 Q2 BIOPHYSICS
Biophysics reviews Pub Date : 2023-03-01 Epub Date: 2023-02-21 DOI:10.1063/5.0131452
Made Harumi Padmaswari, Shilpi Agrawal, Mary S Jia, Allie Ivy, Daniel A Maxenberger, Landon A Burcham, Christopher E Nelson
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引用次数: 0

摘要

杜氏肌营养不良症(DMD)是一种 X 连锁神经肌肉疾病,大约每 5000 个活产男婴中就有一人患病。DMD 由编码肌营养不良蛋白的基因突变引起,而肌营养不良蛋白是肌肉膜稳定所必需的。功能性肌营养不良蛋白的缺失会导致肌肉退化,从而导致虚弱、丧失行动能力、心脏和呼吸系统并发症,最终导致过早死亡。在过去十年中,治疗 DMD 的疗法取得了进展,一些治疗方法已进入临床试验阶段,四种外显子切割药物也获得了美国食品药品管理局的有条件批准。然而,迄今为止,还没有一种治疗方法能提供长期的矫正效果。基因编辑已成为治疗 DMD 的一种前景广阔的方法。目前有多种工具,包括巨核酸酶、锌指核酸酶、转录激活剂样效应核酸酶,最值得注意的是来自细菌适应性免疫系统的RNA引导的聚类规则间隔短回文重复序列(CRISPR)酶。尽管将 CRISPR 用于人类基因治疗仍面临诸多挑战,包括安全性和传递效率,但将 CRISPR 基因编辑用于 DMD 的前景十分广阔。本综述将总结 CRISPR 基因编辑用于 DMD 的进展情况,包括当前方法、传递方法、基因编辑仍面临的挑战以及前瞻性解决方案的主要概述。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Delivery challenges for CRISPR-Cas9 genome editing for Duchenne muscular dystrophy.

Duchene muscular dystrophy (DMD) is an X-linked neuromuscular disorder that affects about one in every 5000 live male births. DMD is caused by mutations in the gene that codes for dystrophin, which is required for muscle membrane stabilization. The loss of functional dystrophin causes muscle degradation that leads to weakness, loss of ambulation, cardiac and respiratory complications, and eventually, premature death. Therapies to treat DMD have advanced in the past decade, with treatments in clinical trials and four exon-skipping drugs receiving conditional Food and Drug Administration approval. However, to date, no treatment has provided long-term correction. Gene editing has emerged as a promising approach to treating DMD. There is a wide range of tools, including meganucleases, zinc finger nucleases, transcription activator-like effector nucleases, and, most notably, RNA-guided enzymes from the bacterial adaptive immune system clustered regularly interspaced short palindromic repeats (CRISPR). Although challenges in using CRISPR for gene therapy in humans still abound, including safety and efficiency of delivery, the future for CRISPR gene editing for DMD is promising. This review will summarize the progress in CRISPR gene editing for DMD including key summaries of current approaches, delivery methodologies, and the challenges that gene editing still faces as well as prospective solutions.

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