The arginine methyltransferase Carm1 is necessary for heart development.

IF 2.2
Sophie Jamet, Seungshin Ha, Tzu-Hua Ho, Scott Houghtaling, Andrew Timms, Kai Yu, Alison Paquette, Ali Murat Maga, Nicholas D E Greene, David R Beier
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Abstract

To discover genes implicated in human congenital disorders, we performed ENU mutagenesis in the mouse and screened for mutations affecting embryonic development. In this work, we report defects of heart development in mice homozygous for a mutation of coactivator-associated arginine methyltransferase 1 (Carm1). While Carm1 has been extensively studied, it has never been previously associated with a role in heart development. Phenotype analysis combining histology and microcomputed tomography imaging shows a range of cardiac defects. Most notably, many affected midgestation embryos appear to have cardiac rupture and hemorrhaging in the thorax. Mice that survive to late gestation show a variety of cardiac defects, including ventricular septal defects, double outlet right ventricle, and persistent truncus arteriosus. Transcriptome analyses of the mutant embryos by mRNA-seq reveal the perturbation of several genes involved in cardiac morphogenesis and muscle development and function. In addition, we observe the mislocalization of cardiac neural crest cells at E12.5 in the outflow tract. The cardiac phenotype of Carm1 mutant embryos is similar to that of Pax3 null mutants, and PAX3 is a putative target of CARM1. However, our analysis does not support the hypothesis that developmental defects in Carm1 mutant embryos are primarily due to a functional defect of PAX3.

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精氨酸甲基转移酶Carm1是心脏发育所必需的。
为了发现与人类先天性疾病有关的基因,我们在小鼠中进行了ENU诱变,并筛选了影响胚胎发育的突变。在这项工作中,我们报告了共激活子相关精氨酸甲基转移酶1 (Carm1)突变的小鼠心脏发育缺陷。虽然Carm1已被广泛研究,但以前从未将其与心脏发育中的作用联系起来。表型分析结合组织学和显微计算机断层成像显示一系列心脏缺陷。最值得注意的是,许多受影响的妊娠中期胚胎出现心脏破裂和胸腔出血。存活到妊娠后期的小鼠表现出多种心脏缺陷,包括室间隔缺陷、双出口右心室和持续性动脉干。通过mRNA-seq对突变胚胎进行转录组分析,揭示了涉及心脏形态发生和肌肉发育和功能的几个基因的扰动。此外,我们还观察到心脏神经嵴细胞在流出道E12.5处的错误定位。Carm1突变体胚胎的心脏表型与Pax3零突变体相似,Pax3可能是Carm1的靶点。然而,我们的分析并不支持Carm1突变胚胎的发育缺陷主要是由于PAX3的功能缺陷的假设。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
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