Targeted AAV gene therapy for neuroblastoma via direct capsid-antibody coupling.

IF 7.9 1区 医学 Q1 MEDICINE, RESEARCH & EXPERIMENTAL
EMBO Molecular Medicine Pub Date : 2026-10-01 Epub Date: 2026-09-12 DOI:10.1038/s44321-026-00520-7
Mirko Luoni, Stefano Parracino, Serena G Giannelli, Francesca Morosi, Elisa Ventura, Agostina Di Pizio, Sharon Muggeo, Angelo Iannielli, Silvia Sicardi, Tamara Canu, Tommaso Russo, Antonio Esposito, Ubaldo Del Carro, Fabio Pastorino, Vania Broccoli
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引用次数: 0

Abstract

Adeno-associated viral (AAV) vectors are widely used in gene therapy for their versatility and safety, but their broad tropism limits cell-specific applications such as targeting primary or metastatic tumor cells. To address this, we developed AAV-STITCH, a strategy using SpyTag technology to covalently attach polypeptides to the AAV capsid. This allows precise, dose-dependent coupling of an anti-GD2 scFv to a galactose-binding-deficient AAV9-W503A capsid, redirecting tropism specifically to GD2-expressing neuroblastoma (NB) cells. In pseudometastatic xenograft mouse models, AAV-STITCHαGD2 selectively transduced NB tumor cells without transduction of healthy liver tissue. Furthermore, delivery of a suicide gene via AAV-STITCHαGD2 significantly slowed tumor growth and extended survival in mice with subcutaneous and pseudometastatic NB xenografts. When combined with standard-of-care chemotherapy for relapsed NB, AAV-STITCHαGD2 produced robust curative effects. Collectively, these results demonstrate the feasibility of engineering AAVs with highly specific transduction properties, providing a versatile platform for targeted tumor cell suppression and advancing the development of next-generation, precision gene therapies for cancer.

通过直接衣壳-抗体偶联靶向AAV基因治疗神经母细胞瘤。
腺相关病毒(AAV)载体因其多功能性和安全性被广泛应用于基因治疗,但其广泛的趋向性限制了细胞特异性应用,如靶向原发性或转移性肿瘤细胞。为了解决这个问题,我们开发了AAV- stitch,这是一种利用SpyTag技术将多肽共价附着在AAV衣壳上的策略。这允许抗gd2 scFv与半乳糖结合缺陷的AAV9-W503A衣壳进行精确的剂量依赖性偶联,特异性地将趋向性重定向到表达gd2的神经母细胞瘤(NB)细胞。在假转移异种移植小鼠模型中,AAV-STITCHαGD2选择性地转导NB肿瘤细胞,而不转导健康肝组织。此外,通过aav - stitch传递自杀基因α gd2显著减缓了皮下和假转移性NB异种移植小鼠的肿瘤生长并延长了生存期。当与标准治疗化疗联合治疗复发性NB时,AAV-STITCHαGD2具有良好的疗效。总之,这些结果证明了具有高度特异性转导特性的工程化aav的可行性,为靶向肿瘤细胞抑制提供了一个通用平台,并推动了下一代精确癌症基因治疗的发展。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
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来源期刊
EMBO Molecular Medicine
EMBO Molecular Medicine 医学-医学:研究与实验
CiteScore
17.70
自引率
0.90%
发文量
105
审稿时长
4-8 weeks
期刊介绍: EMBO Molecular Medicine is an open access journal in the field of experimental medicine, dedicated to science at the interface between clinical research and basic life sciences. In addition to human data, we welcome original studies performed in cells and/or animals provided they demonstrate human disease relevance. To enhance and better specify our commitment to precision medicine, we have expanded the scope of EMM and call for contributions in the following fields: Environmental health and medicine, in particular studies in the field of environmental medicine in its functional and mechanistic aspects (exposome studies, toxicology, biomarkers, modeling, and intervention). Clinical studies and case reports - Human clinical studies providing decisive clues how to control a given disease (epidemiological, pathophysiological, therapeutic, and vaccine studies). Case reports supporting hypothesis-driven research on the disease. Biomedical technologies - Studies that present innovative materials, tools, devices, and technologies with direct translational potential and applicability (imaging technologies, drug delivery systems, tissue engineering, and AI)
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