Muscle mTOR controls iron homeostasis and ferritinophagy via NRF2, HIFs and AKT/PKB signaling pathways.

IF 6.2 2区 生物学 Q1 BIOCHEMISTRY & MOLECULAR BIOLOGY
Agnès Conjard-Duplany, Alexis Osseni, Aline Lamboux, Sandrine Mouradian, Flavien Picard, Vincent Moncollin, Céline Angleraux, Tiphaine Dorel-Dubois, Hélène Puccio, Pascal Leblanc, Bruno Galy, Vincent Balter, Laurent Schaeffer, Yann-Gaël Gangloff
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Abstract

Balanced mTOR activity and iron levels are crucial for muscle integrity, with evidence suggesting mTOR regulates cellular iron homeostasis. In this study, we investigated iron metabolism in muscle-specific mTOR knockout mice (mTORmKO) and its relation to their myopathy. The mTORmKO mice exhibited distinct iron content patterns across muscle types and ages. Slow-twitch soleus muscles initially showed reduced iron levels in young mice, which increased with the dystrophy progression but remained within control ranges. In contrast, the less affected fast-twitch muscles maintained near-normal iron levels from a young age. Interestingly, both mTORmKO muscle types exhibited iron metabolism markers indicative of iron excess, including decreased transferrin receptor 1 (TFR1) and increased levels of ferritin (FTL) and ferroportin (FPN) proteins. Paradoxically, these changes were accompanied by downregulated Ftl and Fpn mRNA levels, indicating post-transcriptional regulation. This discordant regulation resulted from disruption of key iron metabolism pathways, including NRF2/NFE2L2, HIFs, and AKT/PKB signaling. Mechanistically, mTOR deficiency impaired transcriptional regulation of iron-related genes mediated by NRF2 and HIFs. Furthermore, it triggered ferritin accumulation through two NRF2 mechanisms: (1) derepression of ferritin translation via suppression of the FBXL5-IRP axis, and (2) autophagosomal sequestration driven by NCOA4-dependent ferritin targeting to autophagosomes, coupled with age-related impairments of autophagy linked to chronic AKT/PKB activation. Three-week spermidine supplementation in older mTORmKO mice was associated with normalized AKT/PKB-FOXO signaling, increased endolysosomal FTL and reduced total FTL levels in the dystrophic soleus muscle. These findings underscore mTOR's crucial role in skeletal muscle iron metabolism and suggest spermidine as a potential strategy to address impaired ferritinophagy due to autophagy blockade in dystrophic muscle.

肌肉mTOR通过NRF2、hif和AKT/PKB信号通路控制铁稳态和铁蛋白自噬。
平衡的mTOR活动和铁水平对肌肉完整性至关重要,有证据表明mTOR调节细胞铁稳态。在这项研究中,我们研究了肌肉特异性mTOR敲除小鼠(mTORmKO)的铁代谢及其与肌病的关系。mTORmKO小鼠表现出不同肌肉类型和年龄的不同铁含量模式。年轻小鼠的慢抽搐比目鱼肌最初显示铁含量降低,随着营养不良的进展而增加,但仍在控制范围内。相比之下,受影响较小的快速收缩肌肉从小就保持着接近正常的铁水平。有趣的是,两种mTORmKO肌肉类型都表现出铁代谢标志物,表明铁过量,包括转铁蛋白受体1 (TFR1)降低,铁蛋白(FTL)和铁转运蛋白(FPN)蛋白水平升高。矛盾的是,这些变化伴随着Ftl和Fpn mRNA水平的下调,表明转录后调控。这种不协调的调节是由于关键铁代谢途径的破坏,包括NRF2/NFE2L2、hif和AKT/PKB信号。从机制上讲,mTOR缺乏损害了NRF2和hfs介导的铁相关基因的转录调节。此外,它通过两种NRF2机制触发铁蛋白积累:(1)通过抑制FBXL5-IRP轴抑制铁蛋白翻译,以及(2)由ncoa4依赖的铁蛋白靶向自噬体驱动的自噬体隔离,加上与慢性AKT/PKB激活相关的年龄相关的自噬损伤。在老年mTORmKO小鼠中补充三周亚精胺与AKT/PKB-FOXO信号正常化、增加内溶酶体FTL和降低营养不良的比罗鱼肌总FTL水平相关。这些发现强调了mTOR在骨骼肌铁代谢中的关键作用,并提示亚精胺是解决营养不良肌肉自噬阻断导致的铁蛋白自噬受损的潜在策略。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
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来源期刊
Cellular and Molecular Life Sciences
Cellular and Molecular Life Sciences 生物-生化与分子生物学
CiteScore
13.20
自引率
1.20%
发文量
546
审稿时长
1.0 months
期刊介绍: Journal Name: Cellular and Molecular Life Sciences (CMLS) Location: Basel, Switzerland Focus: Multidisciplinary journal Publishes research articles, reviews, multi-author reviews, and visions & reflections articles Coverage: Latest aspects of biological and biomedical research Areas include: Biochemistry and molecular biology Cell biology Molecular and cellular aspects of biomedicine Neuroscience Pharmacology Immunology Additional Features: Welcomes comments on any article published in CMLS Accepts suggestions for topics to be covered
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