A rare cause of neonatal diarrhoea: Microvillositary inclusion disease: about a case report

M. Akhrif, M. Sabib, L. Rouas, T. Meskini, N. Mouane
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Abstract

Microvillositary inclusion disease also known as microvillositary atrophy is a rare congenital enteropathy containing a border abnormality in the brushes of enterocytes, manifesting as severe rebellious diarrhea in newborns and infants. It was first described in 1978 by Davidson, et al. The autosomal recessive mode of transmission is suggested because of the frequency of familial cases and inbreeding. Histopathology plays an essential role in establishing the diagnosis. In 2008, a common mutation was identified in most of the patients studied in the MYO5B gene that codes for the Myosin Vb protein, which helped in understanding the etiopathogeny of this pathology poorly described in the literature. The prognosis for this pathology is extremely bleak, requiring total parenteral nutrition for child survival. Intestinal transplantation is for the moment the only long-term solution. Materials and methods: We report the case of an infant aged 6 months, with no perinatal antecedent. There is 1st degree consanguinity, the mother has a history of deaths in younger siblings in undetermined circumstances. Who since the age of 3 days presents profuse liquid diarrhoea with malnutrition, dehydration and enormous abdominal distension? Several diagnoses were suspected before the jejune biopsy was carried out, which led to the diagnosis of a microvilliositary inclusion disease. The aim of our work is to highlight the rarest cause of neonatal rebel diarrhoea and to know how to include it among other differential diagnoses.
新生儿腹泻的罕见病因:微村庄包涵病1例报告
微绒毛包涵性疾病又称微绒毛萎缩,是一种罕见的先天性肠病,肠细胞刷体边界异常,表现为新生儿和婴儿严重的叛逆性腹泻。1978年,Davidson等人首次描述了它。由于家族病例和近亲繁殖的频繁,常染色体隐性传播模式被建议。组织病理学在确定诊断中起着至关重要的作用。2008年,在大多数被研究的患者中发现了MYO5B基因的共同突变,该基因编码肌球蛋白Vb蛋白,这有助于理解文献中描述较少的这种病理的发病机制。这种病理的预后非常暗淡,需要完全的肠外营养来维持儿童的生存。肠道移植是目前唯一的长期解决方案。材料和方法:我们报告的情况下,6个月大的婴儿,没有围产期先例。有一级血缘关系,母亲有弟弟妹妹在不明情况下死亡的历史。谁从3天大起就出现大量液体腹泻并伴有营养不良、脱水和腹胀?在进行空肠活检之前,有几个诊断被怀疑,这导致了微绒毛组织包涵性疾病的诊断。我们的工作的目的是突出新生儿叛逆腹泻的最罕见的原因,并知道如何将其纳入其他鉴别诊断。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
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