45, X/ 46, X, psu - idic (Y) (q11.2)嵌合现象在原发性闭经合并Swyer综合征的女孩中的应用。

Yu Han, Jiebin Wu, Fangfang Tan, Jing Sha, Bei Zhang, Jingfang Zhai, Xuezhen Wang
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引用次数: 0

摘要

具有46,xy核型的女性特征,历史上称为Swyer综合征,通常分为完全性腺发育不良和部分性腺发育不良。前者完全由46,XY染色体组成,而后者则是45,X/46, XY嵌合的结果。这两种疾病都是性染色体疾病,典型特征是由于胚胎性腺进入睾丸的破坏而导致青春期延迟和原发性闭经。在这篇报道中,我们描述了一个年轻的雌性,通过核型分析,我们发现其基因为45,X [2]/46, X, psu idic (Y) (q11.2)[48]。进一步的拷贝数变异测序(CNV-seq)和荧光原位杂交(FISH)证实了她的染色体改变。随后行性腺切除术和激素替代治疗,月经周期随双侧乳房和子宫发育恢复。在此,我们旨在为临床实践中Swyer综合征患者提供临床管理策略。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

45, X/ 46, X, psu idic (Y) (q11.2) Mosaicism in a Primary Amenorrhea Girl with Swyer Syndrome.

45, X/ 46, X, psu idic (Y) (q11.2) Mosaicism in a Primary Amenorrhea Girl with Swyer Syndrome.

45, X/ 46, X, psu idic (Y) (q11.2) Mosaicism in a Primary Amenorrhea Girl with Swyer Syndrome.

45, X/ 46, X, psu idic (Y) (q11.2) Mosaicism in a Primary Amenorrhea Girl with Swyer Syndrome.

The female characters with a 46, XY karyotype, historically termed Swyer syndrome, are commonly divided into complete and partial gonadal dysgenesis. The former is completely made up of the 46, XY chromosome, while the latter results from 45, X/46, XY mosaicism. Both of them are sex chromosome disorders and are typically characterized by delayed puberty and primary amenorrhea due to disruption of the embryonic gonads into testes. In this report, we described a young female with mos 45, X [2]/46, X, psu idic (Y) (q11.2) [48] by karyotyping. Further copy number variation sequencing (CNV-seq) and fluorescent in situ hybridization (FISH) verified her chromosome alteration. The following gonadectomy and hormone replacement therapy were carried out, and the menstrual cycle recovered along with the development of bilateral breasts and uteruses. Herein, we aim to provide clinical management strategies for the patient with Swyer syndrome in clinical practice.

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