肺表面活性物质代谢功能障碍:一例儿科临床病例报告。

Pub Date : 2024-06-01 Epub Date: 2023-11-23 DOI:10.5546/aap.2023-10084.eng
Carlos Cambaceres, Victoria Viggiano, Camila Parellada, Florencia Esteguy, Sebastián García, Claudio Castaños
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引用次数: 0

摘要

间质性肺病在儿科很少见。它们包括肺表面活性物质代谢功能障碍,肺表面活性物质是一种两亲性分子,可降低表面张力并防止肺泡塌陷。在这里,我们描述了一个6个月大的低体重婴儿的病例,他出现了急性呼吸窘迫和发绀;胸部X光片显示间质浸润、纵隔气肿和双侧肺气肿。在病史记录过程中,注意到他的母亲在1岁时有住院史,诊断不明,需要长期吸氧治疗;她现在有慢性缺氧的迹象。病人住院治疗,需要吸氧治疗。进行了辅助测试以寻找这种情况的病因,但没有阳性结果。胸部计算机断层扫描显示磨玻璃样阴影、间隔间质增厚和空气滞留区域;根据肺活检和基因研究的结果,诊断为肺表面活性物质代谢功能障碍。
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Pulmonary surfactant metabolism dysfunction: A pediatric clinical case report.

Interstitial lung diseases are rare in pediatrics. They include dysfunctions in the metabolism of pulmonary surfactant, an amphipathic molecule that reduces surface tension and prevents alveolar collapse. Here we describe the case of a 6-month-old infant controlled for low weight, who presented with acute respiratory distress and cyanosis; his chest X-ray showed interstitial infiltrate, pneumomediastinum, and bilateral pneumothorax. During history-taking, it was noted that his mother had a history of hospitalization at 1 year old with unknown diagnosis, requiring prolonged oxygen therapy; she now shows signs of chronic hypoxia. The patient was hospitalized and required oxygen therapy. Ancillary tests were done to look for the etiology of the condition, with no positive results. A chest computed tomography showed groundglass opacities, thickening of the septal interstitium, and areas of air trapping; based on the results of a lung biopsy and a genetic study, pulmonary surfactant metabolism dysfunction was diagnosed.

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