遗传性α-胰蛋白酶血症与肥大细胞疾病、运动亢进和自主神经异常相关证据的评估。

IF 2.6 3区 医学 Q2 ALLERGY
Jonathan J Lyons
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引用次数: 0

摘要

自十多年前首次描述以来,我们对遗传性α -胰蛋白酶血症临床影响的理解不断发展。最初被认为是一种遗传性疾病,有一部分患者具有结缔组织异常、自主神经功能障碍症状和肥大细胞激活的综合征表现,我们现在知道遗传性α -胰蛋白酶血症是一种常见的遗传性状和肥大细胞介导反应的修饰因子。最近的研究表明,一些先前认为的与先天性运动过度和体位性心动过速综合征(POTS)的关联是缺乏的,并阐明了以前未被认识到的与克隆和非克隆肥大细胞疾病的关联。随着异四聚体胰蛋白酶的发现和其独特功能活性的证明,胰蛋白酶基因组成的重要性开始受到关注。遗传性α -胰蛋白酶血症存在于α -胰蛋白酶表达谱的末端,并作为该蛋白的自然过表达模型,将胰蛋白酶基因分型作为过敏反应严重程度的遗传生物标志物的潜力摆在了前面。这些数据和未来的研究有望增强我们对胰蛋白酶在健康和疾病中所起作用的理解。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Appraisal of the evidence linking hereditary α-tryptasemia with mast cell disorders, hypermobility and dysautonomia.

Since its first description more than a decade ago, our understanding of the clinical impact of hereditary alpha-tryptasemia has continued to evolve. First considered to be a genetic disorder with a subset of patients having a syndromic presentation composed of connective tissue abnormalities, symptoms of autonomic dysfunction, and findings of mast cell activation, we now know that hereditary alpha-tryptasemia is a common genetic trait and modifier of mast cell-mediated reactions. More recent studies have shown some previously held associations with congenital hypermobility and postural orthostatic tachycardia syndrome (POTS) to be lacking, and illuminated previously unappreciated associations with clonal and nonclonal mast cell disorders. With the discovery of heterotetrameric tryptases and demonstration of their unique functional activities, the importance of tryptase gene composition in general has begun to take focus. Hereditary alpha-tryptasemia exists at the end of a spectrum of alpha-tryptase expression and as a natural overexpression model of this protein, brought to the fore the potential of tryptase genotyping as a genetic biomarker for anaphylaxis severity. These data and future studies hold the promise of enhancing our understanding of the role that tryptases play in health and disease.

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来源期刊
CiteScore
5.70
自引率
35.70%
发文量
106
审稿时长
6-12 weeks
期刊介绍: Allergy & Asthma Proceedings is a peer reviewed publication dedicated to distributing timely scientific research regarding advancements in the knowledge and practice of allergy, asthma and immunology. Its primary readership consists of allergists and pulmonologists. The goal of the Proceedings is to publish articles with a predominantly clinical focus which directly impact quality of care for patients with allergic disease and asthma. Featured topics include asthma, rhinitis, sinusitis, food allergies, allergic skin diseases, diagnostic techniques, allergens, and treatment modalities. Published material includes peer-reviewed original research, clinical trials and review articles.
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