荷兰减少先天性甲状腺功能减退症、先天性肾上腺皮质增生症和枫糖浆尿症新生儿筛查不确定和假阳性结果的价值。

IF 4 Q1 GENETICS & HEREDITY
Rosalie C Martens, Anita Boelen, Michèle H van der Kemp, Annet M Bosch, Eveline M Berghout, Gert Weijman, Nitash Zwaveling-Soonawala, Rendelien K Verschoof-Puite, Robert de Jonge, Sabine E Hannema, Judith E Bosmans, Annemieke C Heijboer
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引用次数: 0

摘要

新生儿筛查(NBS)的不确定和假阳性结果会给父母带来压力,并增加医疗开支。通过改进 NBS 算法可以减少这些结果。荷兰新生儿筛查项目最近针对先天性甲状腺功能减退症(CH)、先天性肾上腺皮质增生症(CAH)和枫糖浆尿症(MSUD)进行了改进。本研究估算了这些改进算法在减少不确定结果和假阳性结果方面的经济效益。针对每种改进算法,分析了不确定/假阳性结果的护理路径。根据不确定结果/假阳性结果的变化,评估了与改进相关的成本,以估算每年减少的成本。改进后,不确定结果和/或假阳性结果减少,而假阴性结果没有增加。对于 CH,假阳性结果每年减少 26 例,相关费用减少 31,156 欧元。对于 CAH,每年可避免 95 次足跟穿刺和 7 例假阳性,相关费用减少 7340 欧元。对于 MSUD,每年可避免 5 例假阳性结果,相关成本减少 11336 欧元。改进后的筛查算法每年可降低成本 49 832 欧元。众所周知,NBS 结果不确定或呈假阳性会对社会心理造成负面影响,因此这些结果凸显了改进 NBS 算法的重要性。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
The Value of Reducing Inconclusive and False-Positive Newborn Screening Results for Congenital Hypothyroidism, Congenital Adrenal Hyperplasia and Maple Syrup Urine Disease in The Netherlands.

Inconclusive and false-positive newborn screening (NBS) results can cause parental stress and increase healthcare expenditures. These results can be reduced by improving NBS algorithms. This was recently done for Congenital Hypothyroidism (CH), Congenital Adrenal Hyperplasia (CAH) and Maple Syrup Urine Disease (MSUD) in the Dutch NBS program. The current study estimates the financial consequences of these improved algorithms related to the reduction in inconclusive results and false-positives. For each improved algorithm, the care pathway of an inconclusive/false-positive result was analyzed. The costs associated with the improvements, based on the change in inconclusive results/false-positives, were assessed to estimate the cost reduction per year. The improvements resulted in a reduction of inconclusive results and/or false-positives, without increasing false-negatives. For CH, false positives decreased by 26 per year with a related cost reduction of EUR 31,156. For CAH, 95 second heel punctures and seven false-positives per year were avoided, leading to a related cost reduction of EUR 7340. For MSUD, five false-positives per year were avoided with a related cost reduction of EUR 11,336. The improved screening algorithms led to a cost reduction of EUR 49,832 annually. Together with the known negative psychosocial effects associated with an inconclusive or false-positive NBS result, these results highlight the importance of improving NBS algorithms.

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来源期刊
International Journal of Neonatal Screening
International Journal of Neonatal Screening Medicine-Pediatrics, Perinatology and Child Health
CiteScore
6.70
自引率
20.00%
发文量
56
审稿时长
11 weeks
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