[溶酶体贮积症--法布里病和戈谢病]。

Deutsche medizinische Wochenschrift (1946) Pub Date : 2024-10-01 Epub Date: 2024-10-09 DOI:10.1055/a-2295-1592
Lucia Segura Schmitz, Julia B Hennermann, André Lollert
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引用次数: 0

摘要

溶酶体贮积症(LSD)是一组因溶酶体功能失常而导致的先天性代谢错误。每 5000 个活产婴儿中就有 1 个患有溶酶体贮积症,尽管每种溶酶体贮积症的发病率都很低。最常见的 LSD 是法布里病和戈谢病。其根本原因主要是酶的缺乏,但也可能是由于转运或激活蛋白的缺陷,从而导致溶酶体内和溶酶体外未降解的贮存物质进行性积累。溶酶体在大分子的降解和细胞循环中发挥着关键作用。除了细胞功能紊乱外,底物积累还可能导致继发性中毒和/或炎症过程。治疗法布里病和戈谢病的几种治疗方法已获批准,包括酶替代疗法、法布里病的伴侣疗法和戈谢病的底物减少疗法。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
[Lysosomal storage disorders - Fabry disease and Gaucher disease].

Lysosomal storage disorders (LSD) are a heterogenous group of inborn errors of metabolism due to lysosomal malfunction. LSDs affect 1 in 5000 live births, albeit every LSD itself has a low incidence. The most common LSDs are Fabry disease and Gaucher disease. The underlying cause mainly is an enzyme deficiency but may also be due to defects in transport or activation proteins, which result in progressive intra- and extra-lysosomal accumulation of undegraded storage material. The lysosomes play a key role in degradation and cellular recycling of macromolecules. Besides disturbance of cellular function, substrate accumulation may result in secondary toxic and/or inflammatory processes. For treatment of Fabry and Gaucher disease, several therapeutic approaches are approved including enzyme replacement therapy, chaperon therapy for Fabry disease and substrate reduction therapy for Gaucher disease.

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