Shao-Jia Mao, Qing-Qing Chen, Yang-Li Dai, Guan-Ping Dong, Chao-Chun Zou
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引用次数: 0
摘要
II型粘多糖病(MPS II)是一种罕见的X连锁隐性遗传溶酶体贮积病。IDS 基因的致病变体会导致伊糖醛酸-2-硫酸酯酶(IDS)的活性降低或丧失,从而导致细胞中的糖胺聚糖(GAG)无法降解,影响细胞功能,最终导致多系统表现,如面部粗糙、多发性骨骼发育不良、反复呼吸道感染和疝气。诊断 MPS II 需要结合临床表现、影像学检查、尿液 GAGs 筛查、酶活性和基因检测。目前,对症治疗是主要的治疗方法。由于经济和药物供应问题,只有少数患者选择酶替代疗法或造血干细胞移植。对该病的认识不足、检测技术不普及、经济发展不平衡等因素导致中国的误诊率和漏诊率居高不下。
The diagnosis and management of mucopolysaccharidosis type II.
Mucopolysaccharidosis type II (MPS II) is a rare X-linked recessive inherited lysosomal storage disease. With pathogenic variants of the IDS gene, the activity of iduronate-2-sulfatase (IDS) is reduced or lost, causing the inability to degrade glycosaminoglycans (GAGs) in cells and influencing cell function, eventually resulting in multisystemic manifestations, such as a coarse face, dysostosis multiplex, recurrent respiratory tract infections, and hernias. Diagnosing MPS II requires a combination of clinical manifestations, imaging examinations, urinary GAGs screening, enzyme activity, and genetic testing. Currently, symptomatic treatment is the main therapeutic approach. Owing to economic and drug availability issues, only a minority of patients opt for enzyme replacement therapy or hematopoietic stem cell transplantation. The limited awareness of the disease, the lack of widespread detection technology, and uneven economic development contribute to the high rates of misdiagnosis and missed diagnosis in China.
期刊介绍:
Italian Journal of Pediatrics is an open access peer-reviewed journal that includes all aspects of pediatric medicine. The journal also covers health service and public health research that addresses primary care issues.
The journal provides a high-quality forum for pediatricians and other healthcare professionals to report and discuss up-to-the-minute research and expert reviews in the field of pediatric medicine. The journal will continue to develop the range of articles published to enable this invaluable resource to stay at the forefront of the field.
Italian Journal of Pediatrics, which commenced in 1975 as Rivista Italiana di Pediatria, provides a high-quality forum for pediatricians and other healthcare professionals to report and discuss up-to-the-minute research and expert reviews in the field of pediatric medicine. The journal will continue to develop the range of articles published to enable this invaluable resource to stay at the forefront of the field.