常染色体隐性共济失调患者的基因调查及 SQSTM1 和 SYNE1 基因两种新型变异的鉴定。

IF 1 Q4 GENETICS & HEREDITY
Diana Mokhtari, Mohammad Jahanpanah, Nasim Jabbari, Hamed Azari, Sana Davarnia, Haleh Mokaber, Sara Arish, Rasol Molatefi, Vahid Abbasi, Behzad Davarnia
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引用次数: 0

摘要

遗传性共济失调症按遗传方式分为常染色体显性遗传、常染色体隐性遗传、X 连锁遗传和线粒体遗传。一大部分成人遗传性共济失调症为常染色体显性遗传,而常染色体隐性小脑共济失调症(ARCA)则较为罕见,其表型和基因型特征具有更大的多样性。因此,全面的基因检测有助于确定ARCA的致病基因。我们通过全外显子组测序在 ARCAs 患者中发现了 SQSTM1 和 SYNE1 基因的两个新型致病变体。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

Genetic investigation of patients with autosomal recessive ataxia and identification of two novel variants in the SQSTM1 and SYNE1 genes.

Genetic investigation of patients with autosomal recessive ataxia and identification of two novel variants in the SQSTM1 and SYNE1 genes.

Hereditary ataxias are classified by inheritance patterns into autosomal dominant, autosomal recessive, X-linked, and mitochondrial modes of inheritance. A large group of adult hereditary ataxias have autosomal dominant inheritance, and autosomal recessive cerebellar ataxias (ARCAs) are rare, with greater diversity in phenotypic and genotypic features. Therefore, comprehensive genetic testing is useful for identifying the genes responsible for ARCAs. We identified two novel pathogenic variants of the SQSTM1 and SYNE1 genes via whole-exome sequencing in patients with ARCAs.

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来源期刊
Human Genome Variation
Human Genome Variation Biochemistry, Genetics and Molecular Biology-Genetics
CiteScore
2.30
自引率
0.00%
发文量
39
审稿时长
13 weeks
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