一名 52 岁女性未确诊的 Shone Complex:病例报告。

IF 0.9 Q3 MEDICINE, GENERAL & INTERNAL
Lila H Abu-Hilal, Yumna Njoum, Duha I Barghouthi, Hasan Khatib, Sameer Mtour, Bilal Adwan
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引用次数: 0

摘要

肖恩复合体(SC)是一种罕见的先天性心脏病,以四种阻塞性畸形为特征,包括伞状二尖瓣(PMV)、左心房瓣上环、主动脉瓣下狭窄和主动脉共动脉瘤。通常情况下,SC 会在生命早期出现。然而,我们遇到了一位 52 岁的女性,26 岁时诊断出高血压,中风后出现左侧肢体无力。她因呼吸困难和心悸加重而就诊,促使我们对她进行了全面检查。超声心动图显示,主动脉瓣双尖瓣严重钙化,主动脉瓣重度狭窄,二尖瓣伞状瓣膜重度狭窄,射血分数保留。心导管检查、主动脉血管造影和非对比胸部计算机断层扫描(CT)显示,后导主动脉突然闭塞,显示主动脉闭塞,侧支血管完善,包括突出的右侧和左侧乳内动脉。因此,她在 52 岁时被诊断为不完全 SC。肖恩复合体是一种罕见的先天性心脏病,通常在儿童早期发病,但也有可能因误诊或检查不完全而导致晚期发病。本病例强调了SC晚期表现的罕见性,并突出了早期诊断和干预对改善预后的重要性。对于出现左侧梗阻性病变的成年患者,应考虑不完全SC。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
An Undiagnosed Shone Complex in a 52-Year-Old Female: A Case Report.

Shone complex (SC) is a rare congenital heart disease characterized by four obstructive anomalies, including parachute mitral valve (PMV), left atrial supra-valvular ring, subaortic stenosis, and coarctation of the aorta. Typically, SC manifests early in life. However, we encountered a 52-year-old female with a history of hypertension diagnosed at 26 years and left-sided weakness poststroke. She presented with worsening dyspnea and palpitations, prompting a thorough investigation. Echocardiography revealed a heavily calcified bicuspid aortic valve with severe aortic stenosis and parachute mitral valve with severe mitral stenosis and preserved ejection fraction, raising suspicions regarding the presence of SC. Cardiac catheterization, aortic-angiography, and noncontrast chest computed tomography (CT) revealed abrupt occlusion of the postductal aorta, giving a picture of aortic coarctation with well-established collateral vessels including prominent right and left internal mammary arteries. So, she was diagnosed with an incomplete SC at the age of 52. Shone complex is a rare congenital heart disease that typically presents in early childhood, but late presentations due to misdiagnosis or incomplete work up are possible. This case emphasizes the rarity of late presentations of SC and highlights the importance of early diagnosis and intervention to improve outcomes. An incomplete SC should be considered in adult patients presenting with left-sided obstructive lesions.

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来源期刊
CiteScore
1.90
自引率
0.00%
发文量
165
审稿时长
12 weeks
期刊介绍: The AFMR is committed to enhancing the training and career development of our members and to furthering its mission to facilitate the conduct of research to improve medical care. Case reports represent an important avenue for trainees (interns, residents, and fellows) and early-stage faculty to demonstrate productive, scholarly activity.
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