蝶窦毛细血管瘤伴鞍区和鞍旁延伸的乳头水肿伴急性深度视力丧失——三种罕见的表现

IF 0.2 4区医学 Q4 CLINICAL NEUROLOGY

Neurology Asia Pub Date : 2023-09-01 DOI:10.54029/2023hxu

Khalilah Mastura Zahari, Nurul 'Ain Masnon, Othmaliza Othman, Kartikasalwah Abd Latif, Noraini Mohd Dusa

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引用次数: 0

摘要

颅内毛细血管瘤(ICH)是罕见的。我们报告一个独特的情况下，一个年轻的男子脑出血谁提出了乳头水肿和急性深度视力丧失。一位27岁的男性，因双侧眼睛视力下降并头痛2周。检查显示视盘肿胀伴严重视力丧失。神经影像学显示血管肿瘤中心位于蝶窦，伴蝶鞍和蝶鞍旁延伸。患者在经蝶窦手术中出现大出血，在手术中进行了动脉内栓塞，随后进行了第二次手术。组织病理学显示为良性毛细血管瘤。视力的改善微乎其微。术后4个月肿瘤复发。脑出血可引起迅速和急性失明。管理是具有挑战性的，有保护的视觉预后。

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Papilledema with acute profound visual loss in capillary haemangioma of the sphenoid sinus with sellar and parasellar extensions – a triple rarity presentation

Intracranial capillary haemangioma (ICH) is rare. We report a unique case of a young man with ICH who was presented with papilledema and acute profound visual loss. A 27-year-old man presented with bilateral eye reduced vision for 2 weeks with headaches. Examination showed optic disc swelling with severe visual loss. Neuroimaging revealed a vascular tumour epicentre at the sphenoid sinus with sellar and parasellar extensions. The patient developed massive bleeding during transsphenoidal surgery, in which intraarterial embolization was done, followed by a second surgery. Histopathology revealed benign capillary haemangioma. There was minimal visual improvement. He then developed tumour recurrence at 4 months postoperatively. ICH may cause rapid and acute blindness. Management is challenging with a guarded visual prognosis.

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来源期刊

Neurology Asia CLINICAL NEUROLOGY-

CiteScore

0.30

自引率

0.00%

发文量

审稿时长

>0 weeks

期刊介绍： Neurology Asia (ISSN 1823-6138), previously known as Neurological Journal of South East Asia (ISSN 1394-780X), is the official journal of the ASEAN Neurological Association (ASNA), Asian & Oceanian Association of Neurology (AOAN), and the Asian & Oceanian Child Neurology Association. The primary purpose is to publish the results of study and research in neurology, with emphasis to neurological diseases occurring primarily in Asia, aspects of the diseases peculiar to Asia, and practices of neurology in Asia (Asian neurology).