Intrinsic contracture of the hands in sarcoid myopathy.

IF 2.2 Q3 RHEUMATOLOGY
Siew Khei Liew, Jin Kyun Park, Hyun Sik Gong
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引用次数: 0

Abstract

Hand involvement in sarcoidosis is rare and it presents as tenosynovitis, dactylitis, nodules and osteoarticular bony destruction. We describe an unusual presentation of progressive intrinsic muscle contracture of both hands in a 42-year-old woman with sarcoid myopathy who presented with painful swelling and weakness of all four extremities. Her systemic symptoms improved with oral corticosteroids, but the hand muscle contracture remained after resolution of myositis. Serial soft tissue releases of intrinsic muscle contracture improved hand function markedly. This case highlights that surgery is a viable option to treat intrinsic muscle contracture in patients with chronic sarcoid myopathy complicated with severe muscle contracture.

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结节性肌病的手部固有挛缩。
结节病很少累及手部,主要表现为腱鞘炎、指突炎、结节和骨关节破坏。我们描述了一个不寻常的表现进行性内在肌肉挛缩的双手在一个42岁的女性与肉瘤肌病谁提出了疼痛肿胀和四肢无力。口服皮质类固醇后全身症状有所改善,但肌炎消退后手部肌肉挛缩仍然存在。连续软组织松解术可明显改善手部功能。本病例强调手术是治疗慢性肉瘤样肌病合并严重肌肉挛缩的患者固有肌肉挛缩的可行选择。
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来源期刊
CiteScore
2.30
自引率
5.00%
发文量
39
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